The article describes the case of cervical myelopathy with tetraparesis and sphincter disorders, as a complication of cervical dystonia in a patient with hyperkinetic form of cerebral palsy. Left-side laterocollis in combination with the same side laterocaput was noted. Myelopathy symptoms progressed gradually over one year. The main clinical problems were: the inability to conduct a qualitative MRI study due to hyperkinesis, which required anesthesia, and the high risk of perioperative complications and relapses of cervical myelopathy. Before the surgery, botulinum therapy of cervical dystonia with abobotulotoxin in the total dose 1000ED was administered that led to regression of hyperkinesis. Microsurgical decompression of the spinal canal with the installation of fixation system at the level of C7-Th1 vertebrae was performed. After surgery, the neck was fixed with a Philadelphia collar. There were no complications after surgery or displacement of the stabilizing structure. This case report indicates the possibility of development of cervical myelopathy in cervical dystonia and demonstrates the need of pre — and post-operative botulinum therapy of cervical dystonia to prevent possible complications and relapses in the postoperative period.