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Kryukov A.I.

Sverzhevsky Research Clinical Institute of Otorhinolaryngology;
Pirogov Russian National Research Medical University

Karpova E.P.

Toropchina L.V.

Russian Medical Academy for Continuous Professional Education

Zelikovich E.I.

Sverzhevsky Research Clinical Institute of Otorhinolaryngology

Rogozhin D.V.

Pirogov Russian National Research Medical University

Donyush E.K.

Pirogov Russian National Research Medical University

Unilateral subjective tinnitus «vanishing bone» disease (Goram—Stout syndrome).

Authors:

Kryukov A.I., Karpova E.P., Toropchina L.V., Zelikovich E.I., Rogozhin D.V., Donyush E.K.

More about the authors

Journal: Russian Bulletin of Otorhinolaryngology. 2022;87(5): 92‑98

DOI: 10.17116/otorino20228705192

Views: 2190

Downloaded: 70

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Table of contents

To cite this article:

Kryukov AI, Karpova EP, Toropchina LV, Zelikovich EI, Rogozhin DV, Donyush EK. Unilateral subjective tinnitus «vanishing bone» disease (Goram—Stout syndrome).. Russian Bulletin of Otorhinolaryngology. 2022;87(5):92‑98. (In Russ.)
https://doi.org/10.17116/otorino20228705192

Подписка 2025 (Russian Bulletin of Otorhinolaryngology)
 
МСФ на ЯМ
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The article presents the case history of an 11-year-old girl with Goram-Stout disease, who debuted with unilateral subjective tinnitus. A review of the literature, cases with damage of the temporal bones and modern methods of treatment of this disease is made.

Keywords:

Gorham-Stout disease
Gorham-Stout syndrome
vanishing bone disease
phantom bone disease
lymphangiogenesis
idiopathic osteolysis
progressive massive osteolysis
temporal bone
unilateral tinnitus
angiogenic bone destruction
sirolimus

Authors:

Kryukov A.I.

Sverzhevsky Research Clinical Institute of Otorhinolaryngology;
Pirogov Russian National Research Medical University

Karpova E.P.

Toropchina L.V.

Russian Medical Academy for Continuous Professional Education

Zelikovich E.I.

Sverzhevsky Research Clinical Institute of Otorhinolaryngology

Rogozhin D.V.

Pirogov Russian National Research Medical University

Donyush E.K.

Pirogov Russian National Research Medical University

Received:

10.02.2022

Accepted:

14.06.2022

List of references:

  1. Jackson J.B.S. A boneless arm. The Boston Medical and Surgical Journal. 1838;18:368-369. 
  2. Gorham LW, Wright AM, Shulz HH, Maxon FC Jr. Disappearing bones, a rare form of massive osteolysis, report of two cases, one of autopsy findings. The American Journal of Medicine. 1954;17(5):7674-7682. https://doi.org/10.1016/0002-9343(54)90027-3
  3. Suero Molina EJ, Niederstadt T, Ruland V, Kayser G, Stummer W, Ewelt C, Rössler J. Cerebrospinal fluid leakage in Gorham-Stout disease due to dura mater involvement after progression of an osteolytic lesion in the thoracic spine. Journal of Neurosurgery. Spine. 2014;21(6):956-960.  https://doi.org/10.3171/2014.8.SPINE131064
  4. Mushkin AYu, Evseev VA, Nikolaev DG, Komissarov MI. A rare variant of angiogenic destruction of a vertebra in a child: Gorhem’s disease? Chirurgiya pozvonochnika. 2014;4:99-105. (In Russ.).
  5. de Keyser CE, Saltzherr MS, Bos EM, Zillikens MC. A Large Skull Defect Due to Gorham—Stout Disease: Case Report and Literature Review on Pathogenesis, Diagnosis, and Treatment. Frontiers in Endocrinology. 2020;11:37.  https://doi.org/10.3389/fendo.2020.00037
  6. Tanoue N, Moedano L, Witte M, Montague M, Lukefahr A, Bernas M. Primary versus trauma-induced Gorham-Stout disease. Lymphology. 2018;51(1):18-27. 
  7. Bocchialini G, Ferrari L, Burlini D. From tooth extraction to Gorham-Stout disease: A case report. International Journal of Surgery Case Reports. 2017;34:110-114.  https://doi.org/10.1016/j.ijscr.2017.03.028
  8. Liang Y, Tian R, Wang J, Shan Y, Gao H, Xie C, Li J, Xu M, Gu S. Gorham-Stout disease successfully treated with sirolimus (rapamycin): a case report and review of the literature. BMC Musculoskeletal Disorders. 2020;21(1):577.  https://doi.org/10.1186/s12891-020-03540-7
  9. Ricci KW, Hammill AM, Mobberley-Schuman P, Nelson SC, Blatt J, Bender JLG, McCuaig CC, Synakiewicz A, Frieden IJ, Adams DM. Efficacy of systemic sirolimus in the treatment of generalized lymphatic anomaly and Gorham-Stout disease. Pediatric Blood and Cancer. 2019;66(5):e27614. https://doi.org/10.1002/pbc.27614
  10. Ozeki M, Nozawa A, Yasue S, Endo S, Asada R, Hashimoto H, Fukao T. The impact of sirolimus therapy on lesion size, clinical symptoms, and quality of life of patients with lymphatic anomalies. Orphanet Journal of Rare Diseases. 2019;14(1):141.  https://doi.org/10.1186/s13023-019-1118-1
  11. Nir V, Guralnik L, Livnat G, Bar-Yoseph R, Hakim F, Ilivitzki A, Bentur L. Propranolol as a treatment option in Gorham-Stout syndrome: a case report. Pediatric Pulmonology. 2014;49(4):417-419.  https://doi.org/10.1002/ppul.22869
  12. Kuriyama DK, McElligott SC, Glaser DW, Thompson KS. Treatment of Gorham-Stout disease with zoledronic acid and interferon-α: a case report and literature review. Journal of Pediatric Hematology/Oncology. 2010;32(8):579-584.  https://doi.org/10.1097/MPH.0b013e3181edb464
  13. Hosoya M, Oishi N, Nishiyama J, Ogawa K. A case report of Gorham-Stout disease diagnosed during the course of recurrent meningitis and cholesteatoma. Journal of Otolaryngology — Head and Neck Surgery. 2020;49(1):18.  https://doi.org/10.1186/s40463-020-00412-x
  14. Morimoto N, Ogiwara H, Miyazaki O, Kitamuara M, Nishina S, Nakazawa A, Maekawa T, Morota N. Gorham-Stout syndrome affecting the temporal bone with cerebrospinal fluid leakage. International Journal of Pediatric Otorhinolaryngology. 2013;77(9):1596-1600. https://doi.org/10.1016/j.ijporl.2013.06.004
  15. Cushing SL, Ishak G, Perkins JA, Rubinstein JT. Gorham-Stout syndrome of the petrous apex causing chronic cerebrospinal fluid leak. Otology and Neurotology. 2010;31(5):789-792.  https://doi.org/10.1097/MAO.0b013e3181de46c5
  16. Hernández-Marqués C, Serrano González A, Cordobés Ortega F, Alvarez-Coca J, Sirvent Cerda S, Carceller Lechón F, Azorín Cuadrillero D. Gorham-Stout disease and cerebrospinal fluid otorrhea. Pediatric Neurosurgery. 2011;47(4):299-302.  https://doi.org/10.1159/000336877
  17. Plontke S, Koitschev A, Ernemann U, Pressler H, Zimmermann R, Plasswilm L. Massive Gorham-Stout osteolysis of the temporal bone and the craniocervical transition. HNO. 2002;50(4):354-357.  https://doi.org/10.1007/s001060100561
  18. Simon F, Luscan R, Khonsari RH, Toubiana J, Belhous K, James S, Blauwblomme T, Zerah M, Denoyelle F, Donadieu J, Couloigner V. Management of Gorham Stout disease with skull-base defects: Case series of six children and literature review. International Journal of Pediatric Otorhinolaryngology. 2019;124:152-156.  https://doi.org/10.1016/j.ijporl.2019.06.002

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